Vici syndrome
W
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Overview
From WUSTL Neuromuscular● Nosology: Immunodeficiency with Cleft lip/palate, Cataract, Hypopigmentation & Absent corpus callosum Epidemiology: 15 patients; Multiple ethnicities Genetics 3 Mutation types: Truncating; Missense & Splice site Homozygous or Compound heterozygous Mutated in human cancer tissue EPG5 protein Functions Autophagy pathway: Clearance of autophagosomal cargo Neuronal embryonic development Expression: CNS, Skeletal & cardiac muscle, Thymus, Immune cells, Lung, Kidneys Mutations Defective autophagy: Reduced fusion of LC3 & NBR1 puncta with lysosomes Normal processing of LC3-I to LC3-II Clinical CNS
OMIM Entries
Related Conditions
Shared genesAcute Motor (Axonal) Neuropathy (AMAN)
IIGQ1BGM1
Bone Morphogenetic Proteins
II
Cell Death/Damage: Mechanisms
MLKLMEMBRANEMLKLRIPK3II
Granulomatous & Inflammatory Myopathies with Anti-mitochondrial antibodies
M2E2CLINICAL
IMPP (Myofasciitis; EVIM) + Deafness: Enterovirus & Hypogammaglobulinemia-Related
D68D71CLINICAL
Phosphoglycerate Kinase Deficiency
DPGPGACLINICAL
External Resources
Data sourced from the Washington University Neuromuscular Disease Center. For clinical use, always refer to primary sources.