Neuromuscular HOMEepAGE
neuromuscular.wustl.edu
/
A–Z

COLQ

Collagen-Like Tail Subunit of Asymmetric Acetylcholinesterase

3p25.1Autosomal RecessiveOMIM 603033
Also known as: CMS5, EAD
W
View full entry on WUSTL Neuromuscular
synmg.html#colq

Gene Summary

RefSeq / NCBI

This gene encodes the subunit of a collagen-like molecule associated with acetylcholinesterase in skeletal muscle. Each molecule is composed of three identical subunits. Each subunit contains a proline-rich attachment domain (PRAD) that binds an acetylcholinesterase tetramer to anchor the catalytic subunit of the enzyme to the basal lamina. Mutations in this gene are associated with endplate acetylcholinesterase deficiency. Multiple transcript variants encoding different isoforms have been found for this gene. [provided by RefSeq, Jul 2008]

Clinical Phenotype

Congenital myasthenic syndrome (CMS) due to acetylcholinesterase (AChE) deficiency at the neuromuscular junction. Fatigable proximal weakness from infancy or early childhood, with pupillary abnormalities. May worsen with acetylcholinesterase inhibitors (pyridostigmine).

Molecular Mechanism

COLQ encodes the collagen tail that anchors asymmetric acetylcholinesterase to the basal lamina of the NMJ. Without the anchor, AChE is absent from the synapse. ACh accumulates, overstimulating and eventually desensitizing the postsynaptic nicotinic receptor — mimicking a cholinergic crisis.

Clinical Hallmarks & Key Evidence

1

COLQ-CMS is uniquely worsened by pyridostigmine (AChE inhibitor) — because there is already no AChE; adding more inhibition causes toxic ACh accumulation and clinical deterioration.

Ohno K et al. Hum Mol Genet. 1998;7(5):807-19.

2

Ephedrine and albuterol are the primary treatments for COLQ-CMS, likely by upregulating AChR or improving NMJ development — bypassing the absent AChE.

Liewluck T et al. Neurology. 2011;77(20):1806-8.

3

Repetitive nerve stimulation in COLQ-CMS shows a characteristic 'double CMAP' (repetitive compound muscle action potential after a single stimulus) due to re-firing from prolonged end-plate potentials.

Engel AG et al. Prog Neurobiol. 2015;131:140-58.

External Resources

WUSTL Neuromuscular
Washington University Disease Center
OMIM
Online Mendelian Inheritance in Man
ClinGen
Clinical Genome Resource
G2P
Gene-to-Phenotype (EBI)
GeneReviews
NCBI Expert-Authored Reviews
NCBI Gene
National Center for Biotechnology Information
PubMed
Biomedical Literature
UniProt
Universal Protein Resource
DECIPHER
DatabasE of genomiC varIation and Phenotype in Humans

Gene data compiled from the Washington University Neuromuscular Disease Center, NCBI Gene, and OMIM. For clinical use, always refer to primary sources.